Calcifying cystic odontogenic tumor accompanied by a dentigerous cyst: A case report

Gamoh,Shoko; Akiyama,Hironori; Furukawa,Chisato; Matsushima,Yuki; Iseki,Tomio; Wato,Masahiro; Tanaka,Akio; Morita,Shosuke; Shimizutani,Kimishige

doi:10.3892/ol.2017.6993

Calcifying cystic odontogenic tumor accompanied by a dentigerous cyst: A case report

Authors:
- Shoko Gamoh
- Hironori Akiyama
- Chisato Furukawa
- Yuki Matsushima
- Tomio Iseki
- Masahiro Wato
- Akio Tanaka
- Shosuke Morita
- Kimishige Shimizutani
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Affiliations: Department of Oral Radiology, Osaka Dental University, Osaka 540‑0008, Japan, First Department of Oral and Maxillofacial Surgery, Osaka Dental University, Osaka 540‑0008, Japan, Department of Oral Pathology, Osaka Dental University, Osaka 573‑1121, Japan
Published online on: September 18, 2017 https://doi.org/10.3892/ol.2017.6993
Pages: 5785-5790
Copyright: © Gamoh et al. This is an open access article distributed under the terms of Creative Commons Attribution License.

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Abstract

A calcifying cystic odontogenic tumor (CCOT) is a proliferation of odontogenic epithelium and scattered nests of ghost cells and calcifications that may form the lining of a cyst, or present as a solid mass. It was previously described by Gorlin et al in 1962 as a calcifying odontogenic cyst. Dentigerous cysts are developmental odontogenic jaw cysts, commonly manifesting in the second and third decades of life. The present study reports an asymptomatic case in a 13‑year‑old boy who was referred to the outpatient clinic of the Osaka Dental University Hospital (Osaka, Japan) for additional investigation of an area of radiolucency in the lower right jaw. X‑ray demonstrated a unilocular, well‑circumscribed, radiolucent lesion in the mandible, which measured 30x20 mm, with radiopaque structures within it. Enucleation of the lesion with tooth extraction was performed, which histopathologically revealed features of a CCOT and a cyst. To the best of our knowledge, the occurrence of such a lesion has not been previously identified. The present study examined the significance of the case with a brief review of the literature.

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